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Abstract
Congenital lingual cyst is rare and there has been no prior case report about prenatally detected lingual cyst in Korea. When a huge oral cyst is observed at prenatal period and can cause life-threatening airway obstruction at birth, ex utero intrapartum treatment (EXIT) procedure is needed to secure the airway. Herein we present a baby with a prenatally detected huge oral cyst. He was delivered safely assisting EXIT procedure and underwent an operation for resection of the cyst from his tongue. The oral cyst was diagnosed as a lingual cyst with rare histologic type consisting mixed gastrointestinal and respiratory epithelium.
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Fig. 1.
Ultrasonography at 26 weeks of gestational age shows a large cystic lesion in oral cavity of fetus (A). MRI at 32 weeks of gestational age also shows a large simple cystic mass (34×31×27 mm, arrow) without solid portion or septal formation (B).
Fig. 3.
The cyst is consisted mixed gastrointestinal and respiratory epithelium. Cystic lining cells are included gastrointestinal cells such as mucus, parietal or chief cells (A, HE stain, × 200). Cystic lining cells are also included ciliated pseudostratified columnar cells (respiratory epithelium) and squamous cells (B, HE stain, ×200).
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