Journal List > J Korean Soc Surg Hand > v.19(4) > 1106473

Lee, Choi, Jung, Kim, and Hwang: A Case of Pachydermodactyly

Abstract

Pachydermodactyly is a form of digital dermal fibromatosis of unknown etiology, characterized by asymptomatic soft tissue swelling on the lateral aspects of the proximal interphalangeal joints of the hands. It usually affects young men and often associated with repetitive mechanical trauma. As a rule, it is a benign condition and a specific therapy or extensive investigation is not necessary in most cases. However, pachydermodactyly is not well recognized by physician. So it can be confused with other rheumatic conditions, such as rheumatoid arthritis or juvenile idiopathic arthritis. A prompt diagnosis is crucial for preventing inappropriate or possible toxic treatment. We describe a case of pachydermodactyly in a 20-year-old military man, who had painless swellings of the hand joints.

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Fig. 1.
Photograph of hands shows bilateral soft tissue swellings of the proximal interphalangeal joints.
jkssh-19-205f1.tif
Fig. 2.
Hand radiograph showings soft tissue swelling around the proximal interphalangeal joints without joint narrowing or bony erosions.
jkssh-19-205f2.tif
Fig. 3.
Magnetic resonance imaging reveals soft tissue swelling of the second to fourth proximal interphalangeal joints of the hand without articular or bony abnormality.
jkssh-19-205f3.tif
Fig. 4.
Skin biopsy specimen exhibits marked hyperkeratosis, acanthosis and thickened dermis with collagen deposition (H&E, ×100).
jkssh-19-205f4.tif
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