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Yi, Park, Park, Park, and Lee: A Case of Relapsing Polychondritis Associated with Ankylosing Spondylitis
Case Report

J Rheum Dis 2015;22(1):56-60.

Published online: 31 October 2015

DOI: https://doi.org/10.4078/jrd.2015.22.1.56

A Case of Relapsing Polychondritis Associated with Ankylosing Spondylitis

Nam Hee Yi, Seung Woon Park, In Seong Park, Chi Hwan Park, Choong Won Lee

Department of Internal Medicine, Wallace Memorial Baptist Hospital, Busan, Korea

Corresponding to: Choong Won Lee, Division of Rheumatology, Department of Internal Medicine, Wallace Memorial Baptist Hospital, 200 Geumdan-ro, Geumjeong-gu, Busan 609-728, Korea. E-mail: nom334@hanmail.net

Received 18 December 2013       Revised 7 May 2014       Accepted 7 May 2014

Copyright © 2015 The Korean College of Rheumatology

This is a Free Access article, which permits unrestricted non-commerical use, distribution, and reproduction in any medium, provided the original work is properly cited.

Abstract

Relapsing polychondritis is an uncommon disease associated with inflammation in cartilaginous tissues throughout the body, particularly affecting the cartilaginous structures of ears, nose, joints, and respiratory tract. Several autoimmune diseases, including vasculitis, are associated with the concurrent relapsing polychondritis. However, ankylosing spondylitis primarily affecting the sacroiliac joints and spine is rare in patients with relapsing polychondritis. We report on a 54-year-old man with con-currently relapsing polychondritis and ankylosing spondylitis.

Keywords: Relapsing polychondritis, Ankylosing spondylitis

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Figure 1.
Deformed ear auricle and saddle nose can be seen.
jrd-22-56f1.tif
Figure 2.
This pelvis anteroposterior shows sclerosis and erosion of both sacroiliiac joints (Grade II).
jrd-22-56f2.tif
Figure 3.
This pelvis anteroposterior shows total loss of joint space and ankylosis of both sacroiliiac joints (Grade III).
jrd-22-56f3.tif
Figure 4.
This 3-dimensional computed tomography shows diffuse stenosis of tracheal lumen and narrowing of both main bronchi, especially left main bronchus is nearly collapsed.
jrd-22-56f4.tif
Table 1.
Reported cases of relapsing polychondritis overlapped with spondyloarthropathy
Study HLA-B27 Sacroiliitis type Overlapped disease
Lee et al. [6] − Bilateral AS
Park et al. [7] ＋ Bilateral AS
Pazirandeh et al. [8] − Bilateral AS
  ＋ Bilateral AS
Bahiri et al. [9] NC Bilateral AS
Johnson et al. [10] NC Bilateral AS
Pearson et al. [3] NC NC Psoriatic arthritis
Raffayová and Rovenský [11] ＋ Bilateral Psoriatic arthritis
Hager and Moore [12] ＋ Bilateral Psoriatic arthritis
Pazirandeh et al. [8] − NC Reiter's syndrome
Hedfors et al. [13] ＋ NC Reiter's syndrome
Silva et al. [14] NC NC Reiter's syndrome

AS: ankylosing spondylitis, NC: not comment.

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