Journal List > J Rheum Dis > v.20(6) > 1064083

Kim, Choi, Lee, and Kang: Spontaneous Esophageal Perforation and Hypopharyngeal Abscess in Adult Dermatomyositis: A Case Report

Abstract

In patients with dermatomyositis, chronic inflammation of the pharynx and esophagus results in coughing and diffi-culty in swallowing. These become important clinical symptoms, especially if they contribute to malnutrition or aspiration pneumonia. They can ultimately reduce the quality of life. In rare cases, if the symptoms worsen despite proper treatment, serious complications may arise, a reason to suspect an esophageal perforation or abscess. The authors report a case of dermatomyositis in an adult patient with rare complications of spontaneous esophageal perforation and hypopharyngeal abscess. The patient received non-surgical treatment and was able to resume oral intake of food.

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Figure 1.
(A) Histopathologic features of an incisional biopsy of the vastus lateralis muscle revealed variation in the fiber sizes and focal perifascicular atrophy, ×40. (B) Muscle fibers showing degene-rating and regenerating changes and perivascular infiltration of lymphohistiocytes, ×200.
jrd-20-381f1.tif
Figure 2.
(A) Computed tomography of the chest showed no remarkable findings in the pharynx in July, 2011. (B) Computed tomography of the chest showed peri-pheral enhancing fluid collection in the inferior aspect of cricoids cartilage, suggesting the presence of an abscess formation in Decem-ber, 2011 (black arrow).
jrd-20-381f2.tif
Figure 3.
(A) Esophagography, revealing the contrast media leakage from the esophagus at the anteriosuperior level of the cricoid cartilage, suggesting an esophageal perforation in December, 2011 (black arrow). (B) Esophagography showing no evidence of the contrast media leakage after 1 month.
jrd-20-381f3.tif
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