Diffuse Idiopathic Skeletal Hyperostosis Associated with Dysphonia and Dysphagia -A Case Report-

Young Joon Ahn; Sung Ho Hahn; Bo Kyu Yang; Seung Rim Yi; Jae Ho Yoo; Dong Jin Yoon; Byung June Chung; Min Hong Zoo; Seong Wan Kim

doi:10.4184/jkss.2006.13.4.327

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Ahn, Hahn, Yang, Yi, Yoo, Yoon, Chung, Zoo, and Kim: Diffuse Idiopathic Skeletal Hyperostosis Associated with Dysphonia and Dysphagia -A Case Report-

Original Article

Journal of Korean Spine Surg 2006;13(4):327-331.

Published online: 21 February 2006

DOI: https://doi.org/10.4184/jkss.2006.13.4.327

Diffuse Idiopathic Skeletal Hyperostosis Associated with Dysphonia and Dysphagia -A Case Report-

Young Joon Ahn, M.D., Sung Ho Hahn, M.D., Bo Kyu Yang, M.D., Seung Rim Yi, M.D., Jae Ho Yoo, M.D., Dong Jin Yoon, M.D., Byung June Chung, M.D., Min Hong Zoo, M.D., Seong Wan Kim, M.D.

Department of Orthopaedic Surgery, National Police Hospital, Seoul, Korea

Address reprint requests to Sung Ho Hahn, M.D. Department of Orthopaedic Surgery, National Police Hospital,#58, Karak-dong, Songpa-gu, Seoul 138-708, Korea Tel: 82-2-3400-1252, Fax: 82-2-449-2120, E-mail: hsh@nph.go.kr

This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/3.0/) which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited.

Abstract

We encountered a rare case of diffuse idiopathic skeletal hyperostosis (DISH) associated with dysphonia and dysphagia. An 80 year-old man developed progressive dysphonia and dysphagia. The radiology study, esophagogram and nasopharyngoscopic exam revealed the esophagus and the posterior wall of the nasopharynx to be severely compressed by the unfused osteophyte of the 3rd and 4th cervical intervertebral space. It was thought that the osteophyte formation was caused by not merely DISH but degenerative changes due to a concentration of stress around the unfused hyperostosis. A resection of the osteophyte was performed, which resolved the clinical symptoms. The followup radiology study, esophagogram and nasopharyngoscopic exam showed that the osteophyte had disappeared.

Keywords: DISH, Cervical spine, Anterior degenerative osteophyte, Dysphonia, Dysphagia

REFERENCES

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Fig. 1.

(A) and (B) Preoperative cervical spine lateral radiograph and sagittal CT scan show contiguous ossification along the anterior aspect of the first (C1) to seventh cervical vertebrae (C7), with a localized osteophyte between C3 and C4.

Fig. 2.

(A) In barium esophagogram, the posterior wall of the hypopharynx is indented by osteophytes and the esophagus is significantly narrowed from C3 to C4. (B) Nasopharyngoscopic view shows mass projecting from posterior wall of hypopharynx.

Fig. 3.

(A) and (B) Postoperative cervical spine lateral radiograph and sagittal CT scan show no osteophytes between C3 and C4.

Fig. 4.

(A) In barium esophagogram, no osteophytes are seen impinging on the posterior wall of the pharynx and contrast media pass-es well through the esophagus. (B) Nasopharyngoscopic view shows widened pharynx without mass.

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