Congenital Bronchoesophageal Fistula with Imperforate Anus and Atrial Septal Defect in a 3-Year-Old Child

Kyong Bok Min; Jong Deok Kim; Min Jung Kim; Kyong Won Kim; Myung Hyun Sohn; Choon Sik Yoon; Dae Yeon Kim; Kyu Earn Kim

doi:10.7581/pard.2012.22.4.428

Journal List > Pediatr Allergy Respir Dis > v.22(4) > 1033206

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Min, Kim, Kim, Kim, Sohn, Yoon, Kim, and Kim: Congenital Bronchoesophageal Fistula with Imperforate Anus and Atrial Septal Defect in a 3-Year-Old Child

Case Report

Pediatric Allergy and Respiratory Disease

Pediatric Allergy and Respiratory Disease 2012; 22(4): 428-432.

Published online: 31 December 2012

DOI: https://doi.org/10.7581/pard.2012.22.4.428

Congenital Bronchoesophageal Fistula with Imperforate Anus and Atrial Septal Defect in a 3-Year-Old Child

Kyong Bok Min, MD¹, Jong Deok Kim, MD¹, Min Jung Kim, MD¹, Kyong Won Kim, MD¹, Myung Hyun Sohn, MD¹, Choon Sik Yoon, MD², Dae Yeon Kim, MD³, Kyu Earn Kim, MD¹

¹Department of Pediatrics, Institute of Allergy, Yonsei University College of Medicine, Seoul, Korea.

²Department of Diagnostic Radiology, Yonsei University College of Medicine, Seoul, Korea.

³Division of Pediatric Surgery, Department of Surgery, Asan Medical Center, University of Ulsan College of Medicine, Seoul, Korea.

Corresponding author (kekim@yuhs.ac)

Received 29 August 2012 Revised 25 September 2012 Accepted 29 October 2012

Abstract

Congenital bronchoesophageal fistula (BEF), congenital communication between esophagus and bronchus, is a rare malformation. Benign BEF shows only nonspecific symptoms that may delay a correct diagnosis and proper treatment. This is a case of a 3-year-old boy presenting congenital BEF with imperforate anus and atrial septal defect. He had recurrent pneumonia in the right lower lobe since he was 5 months old. A barium swallow examination showed a communicating fistula between the lower esophagus and the right lower lobe bronchus. Computed tomography scan supported to delineate the course of the fistula. He underwent resection surgery of the fistula and lobectomy of the right lower lobe. He recovered without any postoperative complications.

Keywords: Bronchoesophageal fistula, Imperforate anus, Atrial septal defect, Recurrent pneumonia

Figures and Tables

Fig. 1

Chest radiography shows multifocal radiolucency in right lower lung field.

Fig. 2

Axial chest computed tomphy reveals unusual approximation between the right bronchus (white arrow) of pathologic area and the dilated air-contained esophagus (black arrow).

Fig. 3

Barium esophagogram demonstrates a fistula (arrow) from the lowesophagus leading to the right lower lobe.

Fig. 4

At dissection, an esophageal bronchus (inner circle) was found 5 mm in diameter and 30 mm in length.

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