Angiolymphoid Hyperplasia with Eosinophilia of Distal Arm

Hong-Kee Yoon; Seong-Hun Kim; Sewha Kim; Ho-Jung Kang

doi:10.4055/jkoa.2013.48.1.49

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Yoon, Kim, Kim, and Kang: Angiolymphoid Hyperplasia with Eosinophilia of Distal Arm

Case Report

Journal of the Korean Orthopaedic Association

Journal of the Korean Orthopaedic Association 2013; 48(1): 49-53.

Published online: 26 February 2013

DOI: https://doi.org/10.4055/jkoa.2013.48.1.49

Angiolymphoid Hyperplasia with Eosinophilia of Distal Arm

Hong-Kee Yoon, M.D., Seong-Hun Kim, M.D.^*, Sewha Kim, M.D.^†, Ho-Jung Kang, M.D.^*

Department of Orthopedic Surgery, Soon Chun Hyang University Seoul Hospital, Soon Chun Hyang University College of Medicine, Seoul, Korea.

^*Department of Orthopedic Surgery, Yonsei University College of Medicine, Seoul, Korea.

^†Department of Pathology, Yonsei University College of Medicine, Seoul, Korea.

Correspondence to: Ho-Jung Kang, M.D. Department of Orthopedic Surgery, Gangnam Severance Hospital, 211, Eonju-ro, Gangnam-gu, Seoul 135-720, Korea. TEL: +82-2-2019-3412, FAX: +82-2-573-5393, Kangho56@yuhs.ac

Received 24 August 2012 Revised 25 October 2012 Accepted 1 November 2012

(open-access):

This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/3.0/) which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited.

Abstract

Angiolymphoid hyperplasia with eosinophilia (ALHE) and Kimura's disease were classified as same disease in the past. Since there are many different clinical and histopathological characteristics that warranted their distinction, they are classified as different disease now. Six cases of Kimura's disease in upper extremity have been reported in Korean literature but ALHE in upper extremity has not been reported yet. We experienced a case of surgically treated ALHE in the upper arm and report this case with review of literature.

Keywords: arm, angiolymphoid hyperplasia, eosinophilia

Figures and Tables

Figure 1

Photographs of the left elbow show soft tissue mass on medial aspect of distal arm.

Figure 2

Magnetic resonance images show 2 enlarged lymph nodes on medial aspect of left upper arm, high signal intensity on fat-suppressed T2-weighted image (A) and marginal enhancement on Gadolinium enhanced fat-suppressed T1-weighted image (B). Severe edema and inflammatory change in surrounding subcutaneous tissue are also observed.

Figure 3

(A) Operative finding and (B) gross finding of the specimen show a gray-pinkish, ill-defined mass which are blended into the surrounding subcutaneous tissue.

Figure 4

Microscopic finding shows vascular proliferation with plump vascular endothelial cell. Infiltration of the numerous lymphocytes and eosinopils around the vascular structure are observed (H&E stain, ×200).

References

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