Journal List > J Korean Ophthalmol Soc > v.55(3) > 1009917

Bae and Kim: Pleomorphic Adenoma of the Lacrimal Gland in a Child

Abstract

Purpose

To report one case of pleomorphic adenoma of the lacrimal gland in a child.

Case summary

A 7-year-old boy presented with a 2-month history of an exophthalmos and mild ptosis of the left eye; there were no other ophthalmologic problems. Orbit MRI revealed a well-defined mass in the left lacrimal gland and a defect in the orbital roof due to pressure erosion. Tumor resection was performed via a lateral orbitotomy and a biopsy was requested. The biopsy revealed tumor tissue that was composed of epithelial elements with variably sized duct formation. Focal squamous metaplasia and keratin production was also observed.

Conclusions

Pleomorphic adenoma of the lacrimal gland should be considered as a differential diagnosis of a lacrimal gland mass in a child.

References

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Figure 1.
Pleomorphic adenoma in a 7-year-old boy who had experienced proptosis and upper eyelid ptosis of left eye for 2 months.
jkos-55-422f1.tif
Figure 2.
(A, B) Magnetic resonance imaging of the orbit revealed an encapsulated ovoid mass (arrow) originating from the lacrimal gland and protruding into the orbit.
jkos-55-422f2.tif
Figure 3.
(A) An encapsulated mass 2.1 × 1.2 × 1.2 cm in size was removed. (B) Histopathologic appearance of the tumor showed the myxomatous matrix and cords of epithelial cells. Duct formation is apparent and secreted eosino-philic material (*) is present in the lumen of the duct (H&E, original magnification × 100). (C) Focal area of squamous metaplasia with keratin formation (K) (H&E, original magnification × 200).
jkos-55-422f3.tif
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