Pleomorphic Adenoma of the Lacrimal Gland in a Child

Ki Woong Bae; Nam Ju Kim

doi:10.3341/jkos.2014.55.3.422

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Bae and Kim: Pleomorphic Adenoma of the Lacrimal Gland in a Child

Original Article

J Korean Ophthalmol Soc 2014;55(3):422-425.

Published online: 7 September 2014

DOI: https://doi.org/10.3341/jkos.2014.55.3.422

Pleomorphic Adenoma of the Lacrimal Gland in a Child

Ki Woong Bae, MD¹, Nam Ju Kim, MD^1,²

¹Department of Ophthalmology, Seoul National University College of Medicine, Seoul, Korea

²Department of Ophthalmology, Seoul National University Bundang Hospital, Seoul National University College of Medicine, Seongnam, Korea

Address reprint requests to Nam Ju Kim, MD Department of Ophthalmology, Seoul National University Bundang Hospital, #82 Gumi-ro 173beon-gil, Bundang-gu, Seongnam 463-707, Korea, Tel: 82-31-787-7376, Fax: 82-31-787-4057, E-mail: resourceful@hanmail.net

Received 24 August 201321 September 2013 Accepted 29 January 2014

This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/3.0/) which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited.

Abstract

Purpose

To report one case of pleomorphic adenoma of the lacrimal gland in a child.

Case summary

A 7-year-old boy presented with a 2-month history of an exophthalmos and mild ptosis of the left eye; there were no other ophthalmologic problems. Orbit MRI revealed a well-defined mass in the left lacrimal gland and a defect in the orbital roof due to pressure erosion. Tumor resection was performed via a lateral orbitotomy and a biopsy was requested. The biopsy revealed tumor tissue that was composed of epithelial elements with variably sized duct formation. Focal squamous metaplasia and keratin production was also observed.

Conclusions

Pleomorphic adenoma of the lacrimal gland should be considered as a differential diagnosis of a lacrimal gland mass in a child.

Keywords: Lacrimal gland tumor, Pediatric, Pleomorphic adenoma

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Figure 1.

Pleomorphic adenoma in a 7-year-old boy who had experienced proptosis and upper eyelid ptosis of left eye for 2 months.

Figure 2.

(A, B) Magnetic resonance imaging of the orbit revealed an encapsulated ovoid mass (arrow) originating from the lacrimal gland and protruding into the orbit.

Figure 3.

(A) An encapsulated mass 2.1 × 1.2 × 1.2 cm in size was removed. (B) Histopathologic appearance of the tumor showed the myxomatous matrix and cords of epithelial cells. Duct formation is apparent and secreted eosino-philic material (*) is present in the lumen of the duct (H&E, original magnification × 100). (C) Focal area of squamous metaplasia with keratin formation (K) (H&E, original magnification × 200).

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