Retinitis Pigmentosa Complicated by Vitreous Hemorrhage in a Young Patient: A Case Report

In Young Chung; Hyoun Do Huh; Seong Jae Kim; Yong Seop Han; Seong Wook Seo; Jong Moon Park

doi:10.3341/jkos.2013.54.8.1293

Journal List > J Korean Ophthalmol Soc > v.54(8) > 1009462

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Chung, Huh, Kim, Han, Seo, and Park: Retinitis Pigmentosa Complicated by Vitreous Hemorrhage in a Young Patient: A Case Report

Original Article

J Korean Ophthalmol Soc 2013;54(8):1293-1297.

Published online: 7 September 2013

DOI: https://doi.org/10.3341/jkos.2013.54.8.1293

Retinitis Pigmentosa Complicated by Vitreous Hemorrhage in a Young Patient: A Case Report

In Young Chung, MD, PhD, Hyoun Do Huh, MD, Seong Jae Kim, MD, Yong Seop Han, MD, PhD, Seong Wook Seo, MD, PhD, Jong Moon Park, MD, PhD

Department of Ophthalmology, Gyeongsang National University School of Medicine, Jinju, Korea

Institute of Health Science, Gyeongsang National University, Jinju, Korea

Address reprint requests to Jong Moon Park, MD, PhD Department of Ophthalmology, Gyeongsang National University Hospital #79 Gangnam-ro, Jinju 660-702, Korea Tel: 82-55-750-8167, Fax: 82-55-758-4158, E-mail: parkjm@gnu.ac.kr

Received 26 January 201313 April 2013 Accepted 27 June 2013

This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/3.0/) which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited.

Abstract

Purpose

To report a case of a young male patient with retinitis pigmentosa (RP) accompanied by vitritis and neo-vascularization of the optic disk in both eyes who underwent unilateral vitrectomy for the treatment of vitreous hemorrhage in the right eye.

Case summary

An 8-year-old boy visited our clinic with a complaint of night blindness. Both eyes showed inflammatory cells in the anterior vitreous and neovascularization of the optic disk confirmed by fluorescein angiography. Extensive vitreous hemorrhage developed in his right eye and he underwent unilateral vitrectomy. His final visual acuity was 0.6 in both eyes.

Conclusions

Vitreous hemorrhage may be related to chronic inflammation in the vitreous and is a very rare RP complication. Vitrectomy can be an effective treatment option for RP complicated by vitreous hemorrhage.

Keywords: Retinitis pigmentosa (RP), Vitrectomy, Vitreous hemorrhage

References

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Figure 1.

(A, B) Fundus photographs show diffuse retinal degeneration with sparing of the macula in both eyes. (C, D) Electroretinograms showing nearly reduced ‘a’ and ‘b’ waves in the both eyes.

Figure 2.

(A, B) Fluorescein angiogram of the both eyes show dye leakage from new vessels around the optic disc margin.

Figure 3.

Fundus photographs show a complete resolusion of the vitreous hemorrhage. (A) Preoperative fundus photograph. (B) Postoperative fundus photograph at 1 month after vitrectomy.

Figure 4.

Humphrey visual field test. The test shows peripheral field constriction of the both eyes.

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