Journal List > Tuberc Respir Dis > v.68(6) > 1001509

Jung, Lee, Lee, Jo, Shin, and Kim: Intralobar Pulmonary Sequestration Receiving Its Blood Supply from the Celiac Artery

Abstract

Intralobar pulmonary sequestration is a rare congenital lung anomaly. It is defined as a portion of nonfunctioning lung parenchyma that receives its blood supply from an anomalous systemic artery. Patients often present with chronic or recurrent pneumonia. A chest radiograph may show a cystic lesion with air-fluid levels in the lung base. A high index of suspicion is needed for a diagnosis. Surgical removal of a symptomatic intralobar pulmonary sequestration is generally the treatment of choice. Identifying the aberrant artery is a difficult problem when resecting a pulmonary sequestration. The thoracic and abdominal aortas are the most common origins for the abnormal blood supply. However, arterial supply from the celiac artery is quite rare. We present a case of intralobar pulmonary sequestration with the blood supply originating from the celiac artery.

Figures and Tables

Figure 1
(A) Chest radiograph on admission showed a patchy consolidation in the left lower hemithorax. (B~D) CT scan of chest revealed irregularly shaped multiloculated cystic consolidation at superior segment and posterior basal segment of left lower lobe.
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Figure 2
(A) CT angiogram showed the prominent aberrant feeder artery arising from the celiac artery (arrow). (B) Selective angiogram revealed a large abnormal artery supplying blood to vessels within the left lower lung, and it was from the celiac artery (arrow). (C) Gross specimen of resected pulmonary sequestration showed multi-cystic and fibrotic changes. (D) Histopathologic finding of pulmonary sequestration showed the bronchiole-like structure lined by ciliated columnar epithelium and systemic arteries with concentrically arranged elastic fibers (H&E stain, ×100).
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