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Kang, Lee, Jeon, Lee, Cha, Park, Park, Jung, and Kim: A Case of Massive Hemoptysis due to Dieulafoy's Disease of the Bronchus
Case Report
Tuberculosis and Respiratory Diseases

Tuberculosis and Respiratory Diseases 2009; 66(1): 58-61.

Published online: 31 January 2009

DOI: https://doi.org/10.4046/trd.2009.66.1.58

A Case of Massive Hemoptysis due to Dieulafoy's Disease of the Bronchus

Yeh Rim Kang, M.D.1, Jung Woo Lee, M.D.1, Hee Jung Jeon, M.D.1, Shin Yeop Lee, M.D.1, Seung Ick Cha, M.D.1, Tae Ihn Park, M.D.2, Jae Yong Park, M.D.1, Tae Hoon Jung, M.D.1, Chang Ho Kim, M.D.1

1Department of Internal Medicine School of Medicine, Kyungpook National University, Daegu, Korea.

2Department of Pathology, School of Medicine, Kyungpook National University, Daegu, Korea.

Address for correspondence: Chang Ho Kim, M.D. Division of Pulmonary and Critical Care Medicine, Department of Internal Medicine, Kyungpook National University Hospital, 50, Samduk 2-ga, Jung-gu, Daegu 700-712, Korea. Phone: 82-53-420-5537, Fax: 82-53-426-2046, kimch@knu.ac.kr

Received 2 December 2008       Accepted 15 January 2009

Copyright©2009. The Korean Academy of Tuberculosis and Respiratory Diseases. All rights reserved.

Abstract

Dieulafoy's disease of the bronchus is rare but potentially life-threatening, and should be considered in patients with massive hemoptysis, especially from unknown etiology. We report a case of a patient with massive hemoptysis due to bronchial Dieulafoy's disease. He underwent bronchial artery embolization and surgical resection, and the post-operative specimen revealed dilated and tortuous arteries in the submucosa that presented as Dieulafoy's disease of the bronchus.

Keywords: Massive hemoptysis, Dieulafoy's disease, Bronchial artery embolization

Figures and Tables

Figure 1
(A) Chest radiograph after endotracheal intubation shows fine nodular densities, mainly in the right lung parenchyma. (B) Six days later, the endotracheal tube was removed and previous parenchymal lesions are almost disappeared.
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Figure 2
(A) Pre-embolization, selective angiography of the right bronchial artery shows contrast leakage into the right bronchial lumen with parenchymal pigmentation. (B) Post-embolization, there is no more leakage of contrast into the bronchial lumen.
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Figure 3
Abnormal, dilated vessel is present in the submucosa beneath the cartilage. Arrows indicate the communicating site between the bronchial lumen (BL) and vascular lumen (VL). (H&E stain, ×20)
trd-66-58-g003

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