Journal List > Tuberc Respir Dis > v.60(6) > 1000967

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Jung, Kim, Park, Han, Kim, Oh, Lee, Choi, Na, Seo, and Kim: 1 Case of Bronchial Leiomyoma with Intralobar Pulmonary Sequestration
Case Report
Tuberculosis and Respiratory Diseases

Tuberculosis and Respiratory Diseases 2006; 60(6): 678-683.

Published online: 30 June 2006

DOI: https://doi.org/10.4046/trd.2006.60.6.678

1 Case of Bronchial Leiomyoma with Intralobar Pulmonary Sequestration

Bo Yong Jung, M.D., Do Hwan Kim, M.D., Eun Seo Park, M.D., Seung Hoe Han, M.D., Young Tong Kim, M.D.1, Mi Hye Oh, M.D.2, Seok Yul Lee, M.D.3, Jae Sung Choi, M.D., Joo Ock Na, M.D., Ki Hyun Seo, M.D., Yong Hoon Kim, M.D.

Department of Internal Medicine, University of Soonchunhyang college of Medicine, Cheonan, Korea.

1Department of Radiology, University of Soonchunhyang college of Medicine, Cheonan, Korea.

2Department of Diagnostic Pathology, University of Soonchunhyang college of Medicine, Cheonan, Korea.

3Department of Thoracic Surgery, University of Soonchunhyang college of Medicine, Cheonan, Korea.

Address for correspondence: Ki Hyun Seo, M.D. Address: 23-20, Bong Myeong-Dong, Cheonan Hospital, Soonchunhyang University Collage of Medicine, Cheonan, 330-721, KOREA. Phone: +82-41-570-3665, Fax: +82-41-574-5762, khseo@schch.co.kr

Received 18 April 2006       Accepted 7 June 2006

Copyright © 2006 The Korean Academy of Tuberculosis and Respiratory Diseases

Abstract

Both bronchial leiomyoma and pulmonary sequestration are rare conditions, and to the best of our knowledge there are no reports of the two conditions coexisting. We report a female patient with bronchial leiomyoma with acquired pulmonary sequestration who presented with dyspnea, cough and purulent sputum. The patient had been treated for pneumonia at a local medical clinic. but was transferred to our clinic beacausr there was no clinical improvement. A 3-D computed tomography scan revealed a 1.5 cm sized mass near the distal portion of the left main bronchus and an anomalous artery arising from the aorta. The patient showed clinical improvement after a left lower lobectomy and a ligation of the anomalous artery.

Keywords: Bronchial leiomyoma, Pulmonary sequestration

Figures and Tables

Figure 1
Chest PA. (A) Initial film shows consolidation on left lower lobe. (B) Follow up film at 1 day on admission shows total collapse of left lung
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Figure 2
Chest CT with CE. (A) Collapse of Left lower lobe due to 1.5 cm sized endobronchial mass (arrow) in distal portion of left main bronchus. (B) Multiple cystic lesion (arrow) at collapse lesion of left lower lobe. (C) Abnormal vessels (arrow) originated from descending aorta at reformed oblique coronal imaging.
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Figure 3
Bronchoscopic finding. (A) An impacted mass-like lesion covered a whitish exudate around the distal main bronchus. (B) At 12 days after operation, there was no endobronchial lesion
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Figure 4
Microscopic finding of pulmonary sequestration. Multicystic spaces lined by cuboidal to columnar epithelium with intervening fibrosis and inflammation (H&E, ×100).
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Figure 5
Microscopic findings of leiomyoma. (A) The tumor is formed by interlacing bundles of spindle cells, which has elongated nuclei and eosinophilic fibrillary cytoplasm (H&E, ×200). (B) Immunohistochemically, the tumor shows a diffuse positive reaction for smooth muscle actin (×200).
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