Infantile cortical hyperostosis (Caffey's disease) is considered to be a benign self- limiting disease of uncertain etiology that appears in early infancy. A 16 month old girl, who had an infantile cortical hyperostosis after her birth, was admitted because of irritability and a painful swelling of her leg and a cortical thickening in her left tibia. We diagnosed this as being a recurrence of infantile cortical hyperostosis according to clincal and radiologic findings. Recurrence of cortical thickening in patient with a history of Caffey's disease may be suspected in the infantile cortical hyperostosis disorder.